Outcome of adult patients with X-linked hypophosphatemia caused by PHEX gene mutations

  • Douglas Chesher
  • , Michael Oddy
  • , Ulpee Darbar
  • , Parag Sayal
  • , Adrian Casey
  • , Aidan Ryan
  • , Annalisa Sechi
  • , Charlotte Simister
  • , Aoife Waters
  • , Yehani Wedatilake
  • , Robin H. Lachmann
  • , Elaine Murphy

Research output: Contribution to journalArticlepeer-review

Abstract

X-linked hypophosphatemia (XLH) is the most common monogenic disorder causing hypophosphatemia. This case-note review documents the clinical features and the complications of treatment in 59 adults (19 male, 40 female) with XLH. XLH is associated with a large number of private mutations; 37 different mutations in the PHEX gene were identified in this cohort, 14 of which have not been previously reported. Orthopaedic involvement requiring surgical intervention (osteotomy) was frequent. Joint replacement and decompressive laminectomy were observed in those older than 40 years. Dental disease (63%), nephrocalcinosis (42%), and hearing impairment (14%) were also common. The rarity of the disease and the large number of variants make it difficult to discern specific genotype-phenotype relationships. A new treatment, an anti-FGF23 antibody, that may affect the natural history of the disease is currently being investigated in clinical trials.

Original languageEnglish
Pages (from-to)865-876
Number of pages12
JournalJournal of Inherited Metabolic Disease
Volume41
Issue number5
DOIs
Publication statusPublished - 1 Sep 2018
Externally publishedYes

Keywords

  • Dental abcess
  • Enthesopathy
  • Nephrocalcinosis
  • Osteotomy
  • PHEX
  • Phosphate regulating endopeptidase homologue
  • X-linked hypophosphatemia
  • XLH

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